[Preconception screening of parents and carrier state of cystic fibrosis in the Netherlands: expenses and savings]

Ned Tijdschr Geneeskd. 1998 Mar 28;142(13):706-10.
[Article in Dutch]

Abstract

Objective: To evaluate effects, costs and savings for a preconceptional couple screening programme for cystic fibrosis (CF) carriers.

Setting: State University Groningen, the Netherlands.

Design: Prospective theoretical evaluation.

Method: A decision tree and an arithmetic model were constructed for two different strategies of preconceptional CF screening of couples: 'single entry two step' (SETS; start by testing one partner), and 'double entry two step' (DETS; test both partners). The difference between costs of screening and costs of CF illness prevented by screening was determined.

Results: DETS couple screening with the assumptions used for e.g. sensitivity and use of options can detect 81.5% of carrier couples in the Netherlands (against 70% for SETS), but results in twice as many positive/negative couples as SETS couple screening. The maximum number of carrier couples identified when screening 100,000 couples would be 88, resulting in a decrease of the number of children with CF of 25 each year. The costs of screening equal the savings if approximately 8,000 couples are screened yearly in the Netherlands.

Conclusions: There are no financial objections to preconceptional couple screening in the Netherlands, even with an uptake ratio of around 10%. Whether screening for CF carriers should be offered or not should be decided on the basis of non-financial arguments.

Publication types

  • English Abstract
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Cost-Benefit Analysis
  • Cystic Fibrosis / prevention & control*
  • Decision Trees
  • Female
  • Genetic Testing / economics*
  • Heterozygote*
  • Humans
  • Male
  • Models, Statistical
  • Netherlands
  • Parents*
  • Prospective Studies
  • Sensitivity and Specificity