Successful treatment of two brothers with congenital afibrinogenemia for splenic rupture using heat- and solvent detergent-treated fibrinogen concentrates

J Pediatr Hematol Oncol. 1997 Sep-Oct;19(5):462-5. doi: 10.1097/00043426-199709000-00011.

Abstract

Purpose: This report describes life-threatening spontaneous splenic rupture in two brothers with congenital afibrinogenemia.

Patients: Two brothers, aged 11 and 14 years, had intra-abdominal bleeding due to splenic rupture confirmed by ECHO ultrasonography and computed tomography scans.

Results: Splenectomy was performed after administration of heat- and solvent-detergent treated fibrinogen concentrates.

Conclusions: Hemostatic treatment for splenic rupture using heat- and solvent detergent-treated fibrinogen concentrates was effective. Careful attention must be paid to the risk of splenic rupture during the growth spurt in physically active children with this rare coagulation disorder.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Afibrinogenemia / complications*
  • Afibrinogenemia / genetics
  • Afibrinogenemia / therapy*
  • Anticoagulants / chemistry
  • Anticoagulants / therapeutic use*
  • Child
  • Detergents
  • Fibrinogen / chemistry
  • Fibrinogen / therapeutic use*
  • Follow-Up Studies
  • Hot Temperature
  • Humans
  • Male
  • Solvents
  • Splenic Rupture / diagnostic imaging
  • Splenic Rupture / etiology
  • Splenic Rupture / therapy*
  • Tomography, X-Ray Computed

Substances

  • Anticoagulants
  • Detergents
  • Solvents
  • Fibrinogen