Parathyroid storm: immediate recognition and pathophysiological considerations

Bone. 1993 Sep-Oct;14(5):703-6. doi: 10.1016/8756-3282(93)90199-k.

Abstract

A 56-year-old white man was referred for evaluation of severe hypercalcemia following a three-week history of progressive weakness, nausea, and depression. Initial laboratory results showed serum total and ionized calcium (Ca++) values of 5.3 and 2.6 mmol/l, respectively. A short intact PTH assay was immediately performed and an extremely high value was obtained in just 30 min (1315 ng/l, normal values 6.4-70.4). The patient was therefore treated with saline solution and with salmon calcitonin (1200 IU/day, half by continuous i.v. infusion and half by i.m. route) for 10 days. There was a sudden decrease of both Ca++ and intact PTH during the first six days; then there was a trend to reach a steady-state until parathyroidectomy was performed. After withdrawal of calcitonin therapy it was possible to observe a positive uncoupling between bone formation (serum alkaline phosphatase and osteocalcin) and resorption (serum tartrate-resistant acid phosphatase) markers. On day 35 the patient underwent neck exploration, and an enlarged lower left parathyroid gland was removed that on macroscopic examination revealed the presence of a haemorrhagic cyst; microscopic appearance was suggestive of a previous glandular infarction. This is the first time the daily clinical course of a parathyroid crisis has been documented. Furthermore, changes of biomarkers of bone turnover following calcitonin therapy show that high doses of the hormone may cause a prolonged positive uncoupling of the two processes of bone remodeling.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Acid Phosphatase / blood
  • Alkaline Phosphatase / blood
  • Biomarkers / blood
  • Bone Remodeling*
  • Calcitonin / administration & dosage
  • Calcitonin / therapeutic use*
  • Calcium / blood*
  • Humans
  • Hypercalcemia / diagnosis
  • Hyperparathyroidism / blood
  • Hyperparathyroidism / diagnosis
  • Hyperparathyroidism / drug therapy
  • Hyperparathyroidism / physiopathology*
  • Infusions, Intravenous
  • Male
  • Middle Aged
  • Osteocalcin / blood
  • Parathyroid Hormone / blood
  • Parathyroidectomy
  • Saline Solution, Hypertonic / administration & dosage
  • Saline Solution, Hypertonic / therapeutic use

Substances

  • Biomarkers
  • Parathyroid Hormone
  • Saline Solution, Hypertonic
  • Osteocalcin
  • salmon calcitonin
  • Calcitonin
  • Alkaline Phosphatase
  • Acid Phosphatase
  • Calcium