Interim analyses of a first-in-human phase 1/2 mRNA trial for propionic acidaemia

Nature. 2024 Apr;628(8009):872-877. doi: 10.1038/s41586-024-07266-7. Epub 2024 Apr 3.

Abstract

Propionic acidaemia is a rare disorder caused by defects in the propionyl-coenzyme A carboxylase α or β (PCCA or PCCB) subunits that leads to an accumulation of toxic metabolites and to recurrent, life-threatening metabolic decompensation events. Here we report interim analyses of a first-in-human, phase 1/2, open-label, dose-optimization study and an extension study evaluating the safety and efficacy of mRNA-3927, a dual mRNA therapy encoding PCCA and PCCB. As of 31 May 2023, 16 participants were enrolled across 5 dose cohorts. Twelve of the 16 participants completed the dose-optimization study and enrolled in the extension study. A total of 346 intravenous doses of mRNA-3927 were administered over a total of 15.69 person-years of treatment. No dose-limiting toxicities occurred. Treatment-emergent adverse events were reported in 15 out of the 16 (93.8%) participants. Preliminary analysis suggests an increase in the exposure to mRNA-3927 with dose escalation, and a 70% reduction in the risk of metabolic decompensation events among 8 participants who reported them in the 12-month pretreatment period.

Publication types

  • Research Support, Non-U.S. Gov't
  • Clinical Trial, Phase I
  • Clinical Trial, Phase II
  • Research Support, N.I.H., Extramural

MeSH terms

  • Administration, Intravenous
  • Adolescent
  • Adult
  • Child
  • Child, Preschool
  • Dose-Response Relationship, Drug
  • Female
  • Humans
  • Infant
  • Male
  • Propionic Acidemia* / genetics
  • Propionic Acidemia* / therapy
  • Propionyl-Coenzyme A Carboxylase* / genetics
  • Propionyl-Coenzyme A Carboxylase* / metabolism
  • RNA, Messenger* / administration & dosage
  • RNA, Messenger* / adverse effects
  • RNA, Messenger* / genetics
  • RNA, Messenger* / therapeutic use
  • Young Adult

Substances

  • Propionyl-Coenzyme A Carboxylase
  • RNA, Messenger