A quarter-century report on neuromyelitis optica spectrum disorder in Thailand: A single-center tertiary care cohort

Mult Scler Relat Disord. 2022 Jul:63:103907. doi: 10.1016/j.msard.2022.103907. Epub 2022 May 22.

Abstract

Background: Neuromyelitis optica spectrum disorder (NMOSD) is an autoimmune demyelinating astrocytopathy with a high relapse-related disability. This is the largest long-term study of Thai NMOSD patients.

Objectives: To compare characteristics and outcomes of aquaporin 4 (AQP4)-IgG-positive and AQP4-IgG-negative patients.

Methods: A retrospective review of NMOSD patients at a university hospital was performed from January 1994 to July 2021.

Results: From 165 NMSOD patients, the overall female-to-male ratio was 14:1. The mean onset age was 37.5 ± 14.3 years, and the median disease duration was 10.2 years. Transverse myelitis (46.1%) and optic neuritis (39.4%) were the most common presentations. Around 60% remained fully ambulatory at the last follow-up. Severe visual loss and ambulation aids were comparable in both groups, but the AQP4-IgG-positive had severe bowel and/or bladder dysfunction more often than the AQP4-IgG-negative (p = 0.026). The mortality rate was 6.7%, mainly from infection. Multivariate analysis showed that longer time-to-diagnosis and higher disability scores were associated with death. Diagnosis within one year yielded better visual and motor outcomes and lower annualized relapse rate.

Conclusions: Thai AQP4-IgG-positive and AQP4-IgG-negative NMOSD patients had similar baseline characteristics. Relapse and mortality rates were comparable to global NMOSD patients. Diagnosis within one year promises better outcomes.

MeSH terms

  • Adult
  • Aquaporin 4
  • Autoantibodies
  • Female
  • Humans
  • Immunoglobulin G
  • Male
  • Middle Aged
  • Myelin-Oligodendrocyte Glycoprotein
  • Neoplasm Recurrence, Local
  • Neuromyelitis Optica* / complications
  • Tertiary Healthcare
  • Thailand / epidemiology
  • Young Adult

Substances

  • Aquaporin 4
  • Autoantibodies
  • Immunoglobulin G
  • Myelin-Oligodendrocyte Glycoprotein