What Has the Undiagnosed Diseases Network Taught Us About the Clinical Applications of Genomic Testing?

Annu Rev Med. 2022 Jan 27:73:575-585. doi: 10.1146/annurev-med-042120-014904.

Abstract

Genetic testing has undergone a revolution in the last decade, particularly with the advent of next-generation sequencing and its associated reductions in costs and increases in efficiencies. The Undiagnosed Diseases Network (UDN) has been a leader in the application of such genomic testing for rare disease diagnosis. This review discusses the current state of genomic testing performed within the UDN, with a focus on the strengths and limitations of whole-exome and whole-genome sequencing in clinical diagnostics and the importance of ongoing data reanalysis. The role of emerging technologies such as RNA and long-read sequencing to further improve diagnostic rates in the UDN is also described. This review concludes with a discussion of the challenges faced in insurance coverage of comprehensive genomic testing as well as the opportunities for a larger role of testing in clinical medicine.

Keywords: RNA sequencing; genetic testing; insurance coverage; long-read sequencing; whole-exome sequencing; whole-genome sequencing.

Publication types

  • Research Support, N.I.H., Extramural
  • Review

MeSH terms

  • Exome
  • Exome Sequencing
  • Genetic Testing
  • Humans
  • Rare Diseases / diagnosis
  • Rare Diseases / genetics
  • Undiagnosed Diseases*