Hi-C detects genomic structural variants in peripheral blood of pediatric leukemia patients

Cold Spring Harb Mol Case Stud. 2022 Jan 10;8(1):a006157. doi: 10.1101/mcs.a006157. Print 2022 Jan.

Abstract

B-cell acute lymphoblastic leukemia (B-ALL) is often driven by chromosome translocations that result in recurrent and well-studied gene fusions. Currently, fluorescent in situ hybridization probes are used to detect candidate translocations in bone marrow samples from B-ALL patients. Recently Hi-C, a sequencing-based technique originally designed to reconstruct the three-dimensional architecture of the nuclear genome, was shown to effectively recognize structural variants. Here, we demonstrate that Hi-C can be used as a genome-wide assay to detect translocations and other structural variants of potential clinical interest. Structural variants were identified in both bone marrow and peripheral blood samples, including an ETV6-RUNX1 translocation present in one pediatric B-ALL patient. Our report provides proof of principle that Hi-C could be an effective strategy to globally detect driver structural variants in B-ALL peripheral blood specimens, reducing the need for invasive bone marrow biopsies and candidate-based clinical tests.

Keywords: hematological neoplasm.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Child
  • Genomic Structural Variation
  • Humans
  • In Situ Hybridization, Fluorescence
  • Oncogene Proteins, Fusion* / genetics
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma* / genetics
  • Translocation, Genetic / genetics

Substances

  • Oncogene Proteins, Fusion

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