CFTR gene variants as a reason for impaired spermatogenesis: a pilot study and a Meta-analysis of published data

Hum Fertil (Camb). 2022 Oct;25(4):728-737. doi: 10.1080/14647273.2021.1900608. Epub 2021 Mar 15.

Abstract

There is increasing data that IVS8-5T variand and TG repeats could lead to impaired spermatogenesis. To investigate this we performed Sanger sequencing on 50 Bulgarian men with a sperm count below 5 × 106/mL and 20 normal fertile men. Frequencies of the results were compared among the two groups. A meta-analysis was perfomed by using the data for 6,423 patients and 5,834 control subjects, tested for the IVS8-5T polymorphism. One case subject (2.0%) was homozygote for the 5 T/5T variant whereas two (4.0%) were heterozygotes for the 5 T/7T variant. No 5 T alleles were found in the control group. The genotypes of the two groups showed a statistically significant difference (p = 0.04, α < 0.05). Also, the odds ratio was 3.73, but this was unsignificant (p = 0.38). All control subjects had 11 TG repeats and for the test group: 47 (94.0%) men with 11 TG repeats and three (6.00%) with 10 TG repeats. Fisher's test showed no significant difference (p = 0.55). The meta-analysis showed that IVS8-5T variant was a risk factor for impaired spermatogenesis (OR = 2.84, p < 0.05) and this was more prominent for non-European (OR = 4.50, p < 0.05) compared to European (OR = 1.28, p < 0.05) men. The IVS8 - 5 T variant could be associated with disorders of sperm production.

Keywords: CFTR; IVS8 – 5T variant; TG repeats; impaired spermatogenesis; meta analysis.

Publication types

  • Meta-Analysis

MeSH terms

  • Alleles
  • Cystic Fibrosis Transmembrane Conductance Regulator* / genetics
  • Female
  • Humans
  • Infertility, Male* / genetics
  • Male
  • Mutation
  • Pilot Projects
  • Semen
  • Spermatogenesis / genetics

Substances

  • Cystic Fibrosis Transmembrane Conductance Regulator
  • CFTR protein, human