Hydroxypropyl Cyclodextrin Improves Amiodarone-induced Aberrant Lipid Homeostasis of Alveolar Cells

Am J Respir Cell Mol Biol. 2021 Apr;64(4):504-514. doi: 10.1165/rcmb.2020-0119OC.

Abstract

Alveolar epithelial type II (AT2) cells secrete pulmonary surfactant via lamellar bodies (LBs). Abnormalities in LBs are associated with pulmonary disorders, including fibrosis. However, high-content screening (HCS) for LB abnormalities is limited by the lack of understanding of AT2 cell functions. In the present study, we have developed LB cells harboring LB-like organelles that secrete surfactant proteins. These cells were more similar to AT2 cells than to parental A549 cells. LB cells recapitulated amiodarone (AMD)-induced LB enlargement, similar to AT2 cells of patients exposed to AMD. To reverse AMD-induced LB abnormalities, we performed HCS of approved drugs and identified 2-hydroxypropyl-β-cyclodextrin (HPβCD), a cyclic oligosaccharide, as a potential therapeutic agent. A transcriptome analysis revealed that HPβCD modulates lipid homeostasis. In addition, HPβCD inhibited AMD-induced LB abnormalities in human induced pluripotent stem cell-derived AT2 cells. Our results demonstrate that LB cells are useful for HCS and suggest that HPβCD is a candidate therapeutic agent for AMD-induced interstitial pneumonia.

Keywords: 2-hydroxypropyl-β-cyclodextrin; alveolar epithelial type 2 cells; amiodarone; high-content screening; lamellar bodies.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • 2-Hydroxypropyl-beta-cyclodextrin / pharmacology*
  • A549 Cells
  • Alveolar Epithelial Cells / drug effects*
  • Alveolar Epithelial Cells / metabolism
  • Alveolar Epithelial Cells / pathology
  • Amiodarone / toxicity*
  • High-Throughput Screening Assays
  • Homeostasis
  • Humans
  • Induced Pluripotent Stem Cells / drug effects*
  • Induced Pluripotent Stem Cells / metabolism
  • Induced Pluripotent Stem Cells / pathology
  • Lipid Metabolism / drug effects*
  • Protein Precursors / metabolism
  • Pulmonary Surfactant-Associated Protein C / metabolism
  • Pulmonary Surfactant-Associated Protein D / metabolism
  • Pulmonary Surfactant-Associated Proteins / metabolism

Substances

  • Protein Precursors
  • Pulmonary Surfactant-Associated Protein C
  • Pulmonary Surfactant-Associated Protein D
  • Pulmonary Surfactant-Associated Proteins
  • SFTPB protein, human
  • SFTPC protein, human
  • 2-Hydroxypropyl-beta-cyclodextrin
  • Amiodarone