CHARACTERIZING THE NATURAL HISTORY OF FOVEAL-SPARING ATROPHIC LATE-ONSET RETINAL DEGENERATION

Retina. 2021 Jun 1;41(6):1329-1337. doi: 10.1097/IAE.0000000000003017.

Abstract

Purpose: To identify quantifiable markers of disease progression in patients with foveal-sparing atrophic late-onset retinal degeneration using fundus autofluorescence and spectral-domain optical coherence tomography imaging.

Methods: Natural history study evaluating patients within a 3-year interval. Disease progression was assessed based on the area of retinal atrophy, macular topographic distribution of lesions, retinal and choroidal thickness and volume, and choroidal vascularity index.

Results: Twenty-four eyes (12 individuals) were included for fundus autofluorescence, and 31 eyes (16 individuals) for spectral-domain optical coherence tomography studies. Measurements were symmetrical between eyes of the same patient. The area of atrophy significantly enlarged (P = 0.002), with a growth rate of 2.67 mm2/year (SD: 2.13; square rooted: 0.57 mm/year, SD = 0.34). Baseline area of atrophy and progression both correlated with age. Most atrophic lesions were found in the temporal macula and progressed nasally at follow-up. Central choroidal and retinal thicknesses and volume in late-onset retinal degeneration cases were significantly reduced compared with controls, but only central retinal thickness decreased significantly at follow-up.

Conclusion: This study identifies the area of atrophy and central retinal thickness, but not chorioretinal volume or choroidal thickness, as markers of short-term progression in late-onset retinal degeneration. These findings may be useful for disease monitoring and late-onset retinal degeneration interventional studies.

Publication types

  • Multicenter Study

MeSH terms

  • Atrophy
  • Choroid / diagnostic imaging
  • Female
  • Fluorescein Angiography / methods*
  • Follow-Up Studies
  • Fovea Centralis / pathology*
  • Fundus Oculi
  • Humans
  • Male
  • Middle Aged
  • Ophthalmoscopy
  • Retinal Degeneration / diagnosis*
  • Retinal Pigment Epithelium / pathology
  • Retrospective Studies
  • Time Factors
  • Tomography, Optical Coherence / methods*
  • Visual Acuity*

Supplementary concepts

  • Late-Onset Retinal Degeneration