Long-read individual-molecule sequencing reveals CRISPR-induced genetic heterogeneity in human ESCs

Genome Biol. 2020 Aug 24;21(1):213. doi: 10.1186/s13059-020-02143-8.

Abstract

Quantifying the genetic heterogeneity of a cell population is essential to understanding of biological systems. We develop a universal method to label individual DNA molecules for single-base-resolution haplotype-resolved quantitative characterization of diverse types of rare variants, with frequency as low as 4 × 10-5, using both short- or long-read sequencing platforms. It provides the first quantitative evidence of persistent nonrandom large structural variants and an increase in single-nucleotide variants at the on-target locus following repair of double-strand breaks induced by CRISPR-Cas9 in human embryonic stem cells.

Keywords: CRISPR-Cas9; Genome editing; Human embryonic stem cell; Long-read sequencing; Nanopore sequencing; Next-generation sequencing; Somatic mutation; Structural variant.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • CRISPR-Associated Protein 9
  • CRISPR-Cas Systems / genetics*
  • Clustered Regularly Interspaced Short Palindromic Repeats*
  • DNA
  • DNA Repair
  • Gene Editing / methods
  • Gene Knock-In Techniques
  • Genetic Heterogeneity*
  • High-Throughput Nucleotide Sequencing / methods
  • Human Embryonic Stem Cells
  • Humans
  • Mutation
  • RNA, Guide, CRISPR-Cas Systems

Substances

  • RNA, Guide, CRISPR-Cas Systems
  • DNA
  • CRISPR-Associated Protein 9