Report of Two Novel Mutations in Indian Patients with Rothmund-Thomson Syndrome

J Pediatr Genet. 2019 Sep;8(3):163-167. doi: 10.1055/s-0039-1684017. Epub 2019 Apr 9.

Abstract

Rothmund-Thomson syndrome (RTS) is a rare autosomal recessive disorder caused by mutations in RECQL4 and has characteristic clinical features. We report two unrelated phenotypically diverse patients (cases 1 and 2) with RTS having novel variants in RECQL4 gene . Case-1 was evaluated for poor growth and recurrent fractures and skin lesions. Case-2 presented at 4 months with failure to thrive and radial ray defect and developed poikilodermatous skin lesions after infancy. Both cases were confirmed to have homozygous pathogenic variants in RECQL4 . Both patients have normal intellect and are on supportive therapy. The presence of characteristic poikiloderma lesions with specific distribution and skeletal anomalies in a patient with proportionate short stature is a clue toward the diagnosis of RTS.

Keywords: RECQL4; Rothmund–Thomson syndrome; poikiloderma.

Publication types

  • Case Reports