Pulmonary Atresia with Ventricular Septal Defect: Rare Presentation with Coronary-to-Pulmonary Artery Collaterals from Both Right and Left Coronaries

World J Pediatr Congenit Heart Surg. 2020 Jul;11(4):NP226-NP228. doi: 10.1177/2150135118825158. Epub 2019 Mar 27.

Abstract

Pulmonary atresia with ventricular septal defect and coronary-dependent pulmonary circulation arising from both major coronary arteries is rare. Dependence of pulmonary blood flow on the coronaries and the risk of early development of pulmonary vascular obstructive disease warrant early surgical repair in these patients. We report a case of a ten-month-old infant with pulmonary atresia with ventricular septal defect and coronary artery-to-main pulmonary artery connections who was successfully managed with ligation of the coronary fistulas and intracardiac repair.

Keywords: collateral blood flow; coronary artery anomaly; fistula; pulmonary atresia with ventricular septal defect.

Publication types

  • Case Reports

MeSH terms

  • Cardiac Surgical Procedures / methods*
  • Collateral Circulation / physiology*
  • Echocardiography
  • Heart Septal Defects / diagnosis*
  • Heart Septal Defects / physiopathology
  • Heart Septal Defects / surgery
  • Humans
  • Infant, Newborn
  • Male
  • Pulmonary Artery / diagnostic imaging
  • Pulmonary Artery / surgery*
  • Pulmonary Atresia / diagnosis*
  • Pulmonary Atresia / physiopathology
  • Pulmonary Atresia / surgery
  • Pulmonary Circulation / physiology*
  • Tomography, X-Ray Computed

Supplementary concepts

  • Pulmonary Atresia With Ventricular Septal Defect