Valproic acid promotes the neuronal differentiation of spiral ganglion neural stem cells with robust axonal growth

Biochem Biophys Res Commun. 2018 Sep 18;503(4):2728-2735. doi: 10.1016/j.bbrc.2018.08.032. Epub 2018 Aug 16.

Abstract

Hearing loss occurs with the loss of hair cells of the cochlea and subsequent degeneration of spiral ganglion neurons (SGNs). Regeneration of SGNs is a potentially promising therapeutic approach to hearing loss in addition to the use of a cochlear implant (CI), because this device stimulates SGNs directly to restore hearing bypassing the missing hair cells. The presence of SGN-neural stem cells (NSCs) has been reported in adult human and mice. These cells have the potential to become SGNs and thus represent a cellular foundation for regeneration therapies for hearing loss. Valproic acid (VPA) has been shown to influence the neural differentiation of NSCs through multiple signaling pathways involving glycogen synthase kinase3β (GSK3β). Our present study therefore aimed to modulate the neural differentiation potential of SGN-NSCs by treatment with VPA. We here report that a clinically relevant concentration of 1 mM VPA induced the differentiation of basic fibroblast growth factor (bFGF)-treated P1- and P14-SGN-NSCs into neuronal and glial cells, confirmed by neuronal marker (Tuj1 and MAP2) and glial cell marker (GFAP and S100β) detection. VPA-treated cells also promoted much longer neurite outgrowth compared to differentiated cells cultured without bFGF. The effects of VPA on the regulation of differentiation may be related to the activation of the Wnt/β-catenin signaling pathway, but not the inhibition of histone deacetylases (HDACs). We propose that VPA has the potential to convert SGN-NSCs into SGNs and thereby restore hearing when combined with a CI.

Keywords: Auditory; Cochlea; Deafness; Hearing loss; Neural stem cells; Spiral ganglion neurons; Valproic acid.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Animals, Newborn
  • Cell Differentiation / drug effects
  • Fibroblast Growth Factor 2 / pharmacology
  • Gene Expression Regulation, Developmental
  • Glial Fibrillary Acidic Protein / genetics
  • Glial Fibrillary Acidic Protein / metabolism
  • Mice
  • Mice, Inbred C57BL
  • Microtubule-Associated Proteins / genetics
  • Microtubule-Associated Proteins / metabolism
  • Neural Stem Cells / drug effects*
  • Neural Stem Cells / metabolism
  • Neural Stem Cells / ultrastructure
  • Neuroglia / drug effects*
  • Neuroglia / metabolism
  • Neuroglia / ultrastructure
  • Neuronal Outgrowth / drug effects*
  • Neuronal Outgrowth / physiology
  • Neurons / drug effects*
  • Neurons / metabolism
  • Neurons / ultrastructure
  • Primary Cell Culture
  • S100 Calcium Binding Protein beta Subunit / genetics
  • S100 Calcium Binding Protein beta Subunit / metabolism
  • Signal Transduction
  • Spiral Ganglion / cytology
  • Spiral Ganglion / drug effects*
  • Spiral Ganglion / metabolism
  • Tubulin / genetics
  • Tubulin / metabolism
  • Valproic Acid / pharmacology*
  • Wnt Proteins / genetics
  • Wnt Proteins / metabolism
  • beta Catenin / genetics
  • beta Catenin / metabolism

Substances

  • CTNNB1 protein, mouse
  • Glial Fibrillary Acidic Protein
  • Microtubule-Associated Proteins
  • Mtap2 protein, mouse
  • S100 Calcium Binding Protein beta Subunit
  • S100b protein, mouse
  • Tubulin
  • Wnt Proteins
  • beta Catenin
  • beta3 tubulin, mouse
  • glial fibrillary astrocytic protein, mouse
  • Fibroblast Growth Factor 2
  • Valproic Acid