Autoimmune GFAP astrocytopathy: Prospective evaluation of 90 patients in 1 year

J Neuroimmunol. 2018 Aug 15:321:157-163. doi: 10.1016/j.jneuroim.2018.04.016. Epub 2018 Apr 27.

Abstract

In this prospective evaluation of serum and CSF samples, all but two CSF GFAPα-IgG positive patients had autoimmune meningoencephalomyelitis while serum GFAPα-IgG positivity alone was less specific. Phenotypes were diverse among patients that were serum positive only. Adult and pediatric clinical presentations were similar. Most patients were immunotherapy responsive. Co-existing NMDA-R-IgG and cancer were associated with lack of response to first-line immunotherapy. Among patients with follow-up information, 18% had relapses. This study demonstrates CSF GFAPα-IgG is a specific autoimmune meningoencephalomyelitis biomarker, with favorable corticosteroid response. Lack of response should prompt evaluation for co-existing NMDA-R-IgG or malignancy.

Keywords: Autoimmune; Cerebrospinal fluid; Glial fibrillary astrocytic protein; Meningoencephalomyelitis; Pediatric.

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Aged, 80 and over
  • Astrocytes / metabolism*
  • Astrocytes / pathology*
  • Autoimmunity / physiology*
  • Biomarkers / blood
  • Biomarkers / cerebrospinal fluid
  • Child
  • Encephalomyelitis / blood
  • Encephalomyelitis / cerebrospinal fluid
  • Encephalomyelitis / diagnosis
  • Female
  • Glial Fibrillary Acidic Protein / blood*
  • Glial Fibrillary Acidic Protein / cerebrospinal fluid*
  • HEK293 Cells
  • Humans
  • Immunoglobulin G / blood
  • Immunoglobulin G / cerebrospinal fluid
  • Male
  • Meningoencephalitis / blood
  • Meningoencephalitis / cerebrospinal fluid
  • Meningoencephalitis / diagnosis
  • Middle Aged
  • Prospective Studies
  • Young Adult

Substances

  • Biomarkers
  • GFAP protein, human
  • Glial Fibrillary Acidic Protein
  • Immunoglobulin G