Isolated Optic Nerve Glioma in Children With and Without Neurofibromatosis: Retrospective Characterization and Analysis of Outcomes

J Child Neurol. 2018 May;33(6):375-382. doi: 10.1177/0883073818758737. Epub 2018 Mar 5.

Abstract

Isolated optic nerve glioma is a rare tumor with no consensus for the best therapeutic approach. Therefore, tumor control and preservation of visual function remain a challenge. In this retrospective study, we describe our experience over 30 years in a single-institutional cohort of children with isolated optic nerve glioma, focusing on treatments and visual outcomes. Seventeen children were followed for a median period of 8 years (range, 2-22 years). Diagnosis was based on typical neuroradiologic findings, and 3 patients had histologic confirmation of their tumors. In our study, conservative management preserved the vision of most patients with neurofibromatosis type 1 (NF1). NF1-related optic nerve gliomas were less often treated but were associated with a lower probability of progression and with occasional spontaneous regression. Sporadic tumors more frequently exhibited aggressive clinical behavior with a higher propensity for posterior extension, often requiring surgical intervention.

Keywords: childhood; isolated optic nerve glioma; neurofibromatosis; sporadic.

Publication types

  • Research Support, N.I.H., Extramural

MeSH terms

  • Adolescent
  • Child
  • Child, Preschool
  • Female
  • Follow-Up Studies
  • Humans
  • Male
  • Neurofibromatoses / complications*
  • Neurofibromatoses / diagnostic imaging
  • Neurofibromatoses / epidemiology
  • Neurofibromatoses / therapy
  • Optic Nerve Glioma / complications*
  • Optic Nerve Glioma / diagnostic imaging
  • Optic Nerve Glioma / epidemiology
  • Optic Nerve Glioma / therapy
  • Retrospective Studies
  • Treatment Outcome
  • Vision Disorders / epidemiology
  • Vision Disorders / etiology
  • Young Adult