Treatment of Pediatric IgG4-Related Orbital Disease With TNF-α Inhibitor

Ophthalmic Plast Reconstr Surg. 2018 Jan/Feb;34(1):e10-e12. doi: 10.1097/IOP.0000000000000959.

Abstract

The authors describe a 9-year-old female who presented with swelling, proptosis, and tenderness of the right upper eyelid and MRI imaging demonstrating right lacrimal gland enlargement. After failing treatment with corticosteroids, the patient underwent a biopsy that was consistent with IgG4-related orbital disease. She was subsequently successfully treated with adalimumab (TNF-α inhibitor). This is the first case report of the successful use of a TNF-α inhibitor for the treatment of IgG4-related orbital disease in a child.

Publication types

  • Case Reports

MeSH terms

  • Adalimumab / therapeutic use*
  • Anti-Inflammatory Agents / therapeutic use
  • Biopsy
  • Child
  • Female
  • Humans
  • Immunoglobulin G / immunology*
  • Magnetic Resonance Imaging
  • Orbital Diseases / diagnosis
  • Orbital Diseases / drug therapy*
  • Orbital Diseases / immunology
  • Tomography, X-Ray Computed
  • Tumor Necrosis Factor-alpha / antagonists & inhibitors*

Substances

  • Anti-Inflammatory Agents
  • Immunoglobulin G
  • Tumor Necrosis Factor-alpha
  • Adalimumab