USP14 inhibitor attenuates cerebral ischemia/reperfusion-induced neuronal injury in mice

J Neurochem. 2017 Mar;140(5):826-833. doi: 10.1111/jnc.13941. Epub 2017 Jan 26.

Abstract

Stroke is associated with over-production of misfolded and aggregating proteins. However, it remains largely unclear whether enhanced removal of protein aggregates following ischemic stroke is neuroprotective. Deubiquitinating enzymes (DUBs) are a large group of proteases that regulate protein degradation. The ubiquitin-specific protease 14 (USP14) is a DUB that is associated with the proteasome and negatively regulates proteasome activity. In this study, we examined the effect of 1-[1-(4-fluorophenyl)-2,5-dimethylpyrrol-3-yl]-2-pyrrolidin-1-ylethanone (IU1), a specific small molecule inhibitor of USP14, on mouse focal cerebral ischemic stroke-induced neuronal injury in mice. We found that IU1 treatment attenuated ischemic stroke-caused neuronal injury, which was reflected by increased survival rate, reduced infarct volume, as well as decreased neuronal loss in the IU1-treated mice compared to the control-treated mice. Additionally, IU1 treatment is associated with reduced protein aggregates and enhanced proteasome functionality. These data not only highlight the significance of protein homeostasis in cerebral ischemia/reperfusion-induced neuronal injury but also extend the therapeutic role of DUB inhibitors.

Keywords: IU1; USP14; deubiquitinating enzymes; ischemia; small molecule inhibitor; stroke.

MeSH terms

  • Animals
  • Behavior, Animal
  • Brain Ischemia / drug therapy*
  • Brain Ischemia / psychology
  • Infarction, Middle Cerebral Artery / pathology
  • Male
  • Mice
  • Mice, Inbred C57BL
  • Neurons / pathology*
  • Neuroprotective Agents / therapeutic use*
  • Protease Inhibitors / therapeutic use*
  • Proteasome Endopeptidase Complex / drug effects
  • Pyrroles / therapeutic use*
  • Pyrrolidines / therapeutic use*
  • Recovery of Function
  • Reperfusion Injury / drug therapy*
  • Reperfusion Injury / psychology
  • Survival Analysis
  • Ubiquitin Thiolesterase / antagonists & inhibitors*

Substances

  • 1-(1-(4-fluorophenyl)-2,5-dimethylpyrrol-3-yl)-2-pyrrolidin-1-ylethanone
  • Neuroprotective Agents
  • Protease Inhibitors
  • Pyrroles
  • Pyrrolidines
  • Usp14 protein, mouse
  • Ubiquitin Thiolesterase
  • Proteasome Endopeptidase Complex