Randomized Trial of Aromatase Inhibitors, Growth Hormone, or Combination in Pubertal Boys with Idiopathic, Short Stature

J Clin Endocrinol Metab. 2016 Dec;101(12):4984-4993. doi: 10.1210/jc.2016-2891. Epub 2016 Oct 6.

Abstract

Context: Growth of short children in puberty is limited by the effect of estrogen on epiphyseal fusion.

Objectives: To compare: 1) the efficacy and safety of aromatase inhibitors (AIs) vs GH vs AI/GH on increasing adult height potential in pubertal boys with severe idiopathic short stature (ISS); and 2) differences in body composition among groups.

Design: Randomized three-arm open-label comparator.

Setting: Outpatient clinical research.

Patients: Seventy-six pubertal boys [mean (SE) age, 14.1 (0.1) years] with ISS [height SD score (SDS), -2.3 (0.0)].

Intervention: Daily AIs (anastrozole or letrozole), GH, or AI/GH for 24-36 months.

Outcomes: Anthropometry, bone ages, dual x-ray absorptiometry, spine x-rays, hormones, safety labs.

Results: Height gain [mean (SE)] at 24 months was: AI, +14.0 (0.8) cm; GH, +17.1 (0.9) cm; AI/GH, +18.9 (0.8) cm (P < .0006, analysis of covariance). Height SDS was: AI, -1.73 (0.12); GH, -1.43 (0.14); AI/GH, -1.25 (0.12) (P < .0012). Those treated through 36 months grew more. Regardless of treatment duration, height SDS at near-final height [n = 71; age, 17.4 (0.2) years; bone age, 15.3 (0.1) years; height achieved, ∼97.6%] was: AI, -1.4 (0.1); GH, -1.4 (0.2); AI/GH, -1.0 (0.1) (P = .06). Absolute height change was: AI, +18.2 (1.6) cm; GH, +20.6 (1.5) cm; AI/GH, +22.5 (1.4) cm (P = .01) (expected height gain at -2.0 height SDS, +13.0 cm). AI/GH had higher fat free mass accrual. Measures of bone health, safety labs, and adverse events were similar in all groups. Letrozole caused higher T and lower estradiol than anastrozole.

Conclusions: Combination therapy with AI/GH increases height potential in pubertal boys with ISS more than GH and AI alone treated for 24-36 months with a strong safety profile.

Publication types

  • Randomized Controlled Trial

MeSH terms

  • Adolescent
  • Anastrozole
  • Aromatase Inhibitors / administration & dosage
  • Aromatase Inhibitors / adverse effects
  • Aromatase Inhibitors / pharmacology*
  • Body Composition*
  • Body Height / drug effects*
  • Drug Therapy, Combination
  • Dwarfism / diagnostic imaging
  • Dwarfism / drug therapy*
  • Growth Hormone / administration & dosage
  • Growth Hormone / adverse effects
  • Growth Hormone / pharmacology*
  • Humans
  • Letrozole
  • Male
  • Nitriles / administration & dosage
  • Nitriles / adverse effects
  • Nitriles / pharmacology
  • Outcome Assessment, Health Care*
  • Puberty*
  • Triazoles / administration & dosage
  • Triazoles / adverse effects
  • Triazoles / pharmacology

Substances

  • Aromatase Inhibitors
  • Nitriles
  • Triazoles
  • Anastrozole
  • Letrozole
  • Growth Hormone