Development of acute lymphoblastic leukemia with IgH-EPOR in a patient with secondary erythrocytosis

Int J Hematol. 2016 Dec;104(6):741-743. doi: 10.1007/s12185-016-2083-2. Epub 2016 Aug 20.

Abstract

We report the first patient to develop ALL with a fusion gene of the erythropoietin receptor (EPOR) with immunoglobulin heavy chain (IgH) 22 years after a diagnosis of secondary erythrocytosis with unknown etiology. The IgH-EPOR rearrangement is known to induce increased expression of EPOR, and activates EPO-associated signal pathways by exogenous EPO stimulation, resulting in the increased proliferation and survival of IgH-EPOR-positive leukemic cells. Interestingly, this case may provide supporting the possibility that IgH-EPOR-positive ALL has a growth advantage under sustained high concentrations of EPO.

Keywords: Acute lymphoblastic leukemia; IgH-EPOR; Secondary erythrocytosis.

Publication types

  • Case Reports

MeSH terms

  • Child
  • Gene Fusion
  • Humans
  • Immunoglobulin Heavy Chains / genetics*
  • Male
  • Polycythemia / complications*
  • Polycythemia / genetics*
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma / complications*
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma / genetics*
  • Receptors, Erythropoietin / genetics*

Substances

  • Immunoglobulin Heavy Chains
  • Receptors, Erythropoietin