Detection and prognostic value of recurrent exportin 1 mutations in tumor and cell-free circulating DNA of patients with classical Hodgkin lymphoma

Haematologica. 2016 Sep;101(9):1094-101. doi: 10.3324/haematol.2016.145102. Epub 2016 Jun 13.

Abstract

Classical Hodgkin lymphoma is one of the most common lymphomas and shares clinical and genetic features with primary mediastinal B-cell lymphoma. In this retrospective study, we analyzed the recurrent hotspot mutation of the exportin 1 (XPO1, p.E571K) gene, previously identified in primary mediastinal B-cell lymphoma, in biopsies and plasma circulating cell-free DNA from patients with classical Hodgkin lymphoma using a highly sensitive digital PCR technique. A total of 94 patients were included in the present study. This widely expressed XPO1 E571K mutation is present in one quarter of classical Hodgkin lymphoma patients (24.2%). Mutated and wild-type classical Hodgkin lymphomas were similar regarding the main clinical features. Patients with a detectable XPO1 mutation at the end of treatment displayed a tendency toward shorter progression-free survival, as compared to patients with undetectable mutation in plasma cell-free DNA (2-year progression-free survival: 57.1%, 95% confidence interval: 30.1-100% versus 2-year progression-free survival: 90.5%, 95% confidence interval: 78.8-100%, respectively, P=0.0601). To conclude, the detection of the XPO1 E571K mutation in biopsy and plasma cell-free DNA by digital PCR may be used as a novel biomarker in classical Hodgkin lymphoma for both diagnosis and minimal residual disease, and pinpoints a crucial role of XPO1 in classical Hodgkin lymphoma pathogenesis. The detection of somatic mutation in the plasma cell-free DNA of patients represents a major technological advance in the context of liquid biopsies and noninvasive management of classical Hodgkin lymphoma.

MeSH terms

  • Adult
  • Amino Acid Substitution
  • Biomarkers, Tumor
  • Cell Line, Tumor
  • Codon
  • Combined Modality Therapy
  • DNA, Neoplasm / blood
  • DNA, Neoplasm / genetics*
  • Exportin 1 Protein
  • Female
  • High-Throughput Nucleotide Sequencing
  • Hodgkin Disease / diagnosis*
  • Hodgkin Disease / genetics*
  • Hodgkin Disease / mortality
  • Hodgkin Disease / therapy
  • Humans
  • Karyopherins / genetics*
  • Male
  • Middle Aged
  • Mutation*
  • Neoplasm Staging
  • Neoplasms / diagnosis*
  • Neoplasms / genetics*
  • Neoplasms / mortality
  • Neoplasms / therapy
  • Positron Emission Tomography Computed Tomography
  • Prognosis
  • Receptors, Cytoplasmic and Nuclear / genetics*
  • Recurrence
  • Retrospective Studies
  • Survival Analysis
  • Treatment Outcome
  • Tumor Burden
  • Young Adult

Substances

  • Biomarkers, Tumor
  • Codon
  • DNA, Neoplasm
  • Karyopherins
  • Receptors, Cytoplasmic and Nuclear