Technical aspects and effectiveness of percutaneous fetal therapies for large sacrococcygeal teratomas: cohort study and literature review

Ultrasound Obstet Gynecol. 2016 Jun;47(6):712-9. doi: 10.1002/uog.14935.

Abstract

Objectives: The objectives of this study were to evaluate the efficacy of minimally invasive ablation of high-risk large sacrococcygeal teratomas (SCT) and to compare the efficacy of vascular and interstitial tumor ablation.

Methods: This was a retrospective multicenter study including a cohort of fetuses with high-risk large SCTs between 2004 and 2010. In addition, we performed a systematic literature review of all cases that underwent tumor ablation in order to compare the survival rates after 'vascular' and 'interstitial' ablation. Statistical analysis was conducted using Bayesian methods.

Results: In our cohort, a total of 13 fetuses had high-risk large SCT and five of them underwent tumor ablation. The estimated difference in hydrops resolution rate between the fetal intervention and the no fetal intervention groups was 44.6% (95% credibility interval, 1.5 to 81.0%; Pdiff> 0 = 97.9%). The estimated difference in survival rate between the fetal intervention and the no fetal intervention groups was 31.0% (13.9 to 48.1%; Pdiff> 0 = 99.9%). We analyzed our five cases together with 28 cases from the literature and estimated the difference in survival rate between the vascular and interstitial ablation groups as 19.8% (-13.1 to 50.1%; Pdiff> 0 = 88.3%). The estimated difference in hydrops resolution rate between the vascular and the interstitial ablation groups was 36.7% (-5.7 to 72.7%; Pdiff> 0 = 95.5%).

Conclusion: Minimally invasive surgery seems to improve perinatal outcome in cases of high-risk large fetal SCT. Our findings suggest that 'vascular' ablation may improve outcome and may be more effective than 'interstitial' tumor ablation, but this hypothesis needs further investigation in a larger multicenter prospective study. Copyright © 2015 ISUOG. Published by John Wiley & Sons Ltd.

Keywords: fetal surgery; sacrococcygeal teratoma; tumor interstitial ablation; vascular ablation.

Publication types

  • Multicenter Study
  • Review
  • Systematic Review

MeSH terms

  • Ablation Techniques / methods*
  • Ablation Techniques / mortality
  • Cohort Studies
  • Female
  • Fetal Therapies / methods*
  • Humans
  • Minimally Invasive Surgical Procedures / methods
  • Pregnancy
  • Retrospective Studies
  • Sacrococcygeal Region
  • Spinal Neoplasms / surgery*
  • Survival Analysis
  • Teratoma / surgery*
  • Treatment Outcome