Cytoreductive conditioning for severe combined immunodeficiency--help or hindrance?

Expert Rev Clin Immunol. 2015;11(7):785-8. doi: 10.1586/1744666X.2015.1041926.

Abstract

Use of chemotherapy-based conditioning-facilitated engraftment in patients with severe combined immunodeficiency (SCID) is contentious. In T- and NK lymphocyte-negative, B-lymphocyte-positive (T-B+NK+) and T-B-NK+ SCID, the osteo-medullary space is occupied by recipient hematopoietic stem cells and mature B-lymphocytes. The thymic niche is empty in T-B+NK+ SCID but fully occupied by developmentally arrested T-lymphocyte precursors in T-B-NK+ SCID. The outcome of infusion of donor stem cells differs and is dependent on genetic defect and the lymphocyte developmental arrest stage. At best, donor hematopoietic stem cell osteo-medullary engraftment induces normal B-lymphocyte function and long-term thymopoiesis; at worst, peripheral expansion of donor T-lymphocytes from the stem cell source results in a restricted T-lymphocyte receptor repertoire with possible B-lymphocyte failure. Conditioning improves immunoreconstitution but causes short- and long-term toxicities, and increased mortality. Newborn screening for SCID will propel the search for safe, effective methods of achieving donor cell engraftment and full immunoreconstitution without toxic sequalae.

Keywords: chemotherapy conditioning; hematopoietic stem cell transplantation; severe combined immunodeficiency; thymopoiesis.

Publication types

  • Editorial

MeSH terms

  • Allografts
  • Animals
  • B-Lymphocytes / immunology*
  • B-Lymphocytes / pathology
  • Hematopoietic Stem Cell Transplantation*
  • Humans
  • Lymphocyte Depletion*
  • Portraits as Topic
  • Severe Combined Immunodeficiency* / immunology
  • Severe Combined Immunodeficiency* / pathology
  • Severe Combined Immunodeficiency* / therapy
  • T-Lymphocytes / immunology*
  • T-Lymphocytes / pathology
  • Transplantation Conditioning / methods*