Atrx promotes heterochromatin formation at retrotransposons

EMBO Rep. 2015 Jul;16(7):836-50. doi: 10.15252/embr.201439937. Epub 2015 May 26.

Abstract

More than 50% of mammalian genomes consist of retrotransposon sequences. Silencing of retrotransposons by heterochromatin is essential to ensure genomic stability and transcriptional integrity. Here, we identified a short sequence element in intracisternal A particle (IAP) retrotransposons that is sufficient to trigger heterochromatin formation. We used this sequence in a genome-wide shRNA screen and identified the chromatin remodeler Atrx as a novel regulator of IAP silencing. Atrx binds to IAP elements and is necessary for efficient heterochromatin formation. In addition, Atrx facilitates a robust and largely inaccessible heterochromatin structure as Atrx knockout cells display increased chromatin accessibility at retrotransposons and non-repetitive heterochromatic loci. In summary, we demonstrate a direct role of Atrx in the establishment and robust maintenance of heterochromatin.

Keywords: Atrx; Daxx; IAP retrotransposons; heterochromatin; histone H3.3.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Chromatin Assembly and Disassembly
  • DNA Helicases / genetics*
  • DNA Helicases / metabolism*
  • Genes, Intracisternal A-Particle*
  • Genomic Instability
  • Heterochromatin / genetics
  • Heterochromatin / metabolism*
  • Nuclear Proteins / genetics*
  • Nuclear Proteins / metabolism*
  • RNA Interference
  • RNA, Small Interfering
  • X-linked Nuclear Protein

Substances

  • Heterochromatin
  • Nuclear Proteins
  • RNA, Small Interfering
  • DNA Helicases
  • Atrx protein, mouse
  • X-linked Nuclear Protein