Creation of a neovagina in a patient with Mayer-Rokitansky-Küster-Hauser (MRKH) syndrome and previously corrected rectovestibular fistula concomitant with imperforate anus

J Pediatr Adolesc Gynecol. 2015 Apr;28(2):e17-9. doi: 10.1016/j.jpag.2014.04.003. Epub 2014 Apr 24.

Abstract

Background: Congenital absence of uterus and vagina (CAUV) when associated with anorectal malformations is usually diagnosed and repaired in infancy at the time of anorectoplasty. Long-term observations of patients are scarce and do not justify early vaginal reconstruction. Question arises whether creation of a neovagina can be safely and successfully performed when the patient is mature.

Case: The patient, diagnosed with MRKH syndrome at 16 years of age, underwent repair of rectovestibular fistula and imperforate anus ("cut-back" procedure, temporal sigmostomy and sagittal anterior anorectoplasty) in infancy. At 18, modified Wharton vaginoplasty was performed with a good anatomico-functional outcome.

Summary and conclusions: Early repair of anorectal malformation and postponed vaginal reconstruction seem to be a viable option for patients with congenital rectovestibular fistula and anal atresia concomitant with CAUV.

Keywords: Anal atresia; Anorectal malformation; Mayer-rokitansky-kuster-hauser syndrome; Vaginal aplasia.

Publication types

  • Case Reports

MeSH terms

  • 46, XX Disorders of Sex Development / complications
  • 46, XX Disorders of Sex Development / surgery*
  • Adolescent
  • Anus, Imperforate / complications
  • Anus, Imperforate / surgery*
  • Congenital Abnormalities / surgery*
  • Female
  • Humans
  • Mullerian Ducts / abnormalities*
  • Mullerian Ducts / surgery
  • Plastic Surgery Procedures / methods*
  • Rectovaginal Fistula / complications
  • Rectovaginal Fistula / surgery*
  • Vagina / abnormalities
  • Vagina / surgery*

Supplementary concepts

  • Mullerian aplasia