Sudden arrhythmic death syndrome: diagnostic yield of comprehensive clinical evaluation of pediatric first-degree relatives

Pacing Clin Electrophysiol. 2014 Dec;37(12):1681-5. doi: 10.1111/pace.12479. Epub 2014 Aug 19.

Abstract

Aims: Sudden arrhythmic death syndrome (SADS) is most often caused by heritable cardiac diseases. Studies in adults have identified evidence of inherited cardiovascular diseases in up to 53% of families, but data on the prevalence of familial disease in children are scarce. The aim of this study was to evaluate the yield of clinical screening in pediatric first-degree relatives of victims of SADS using a systematic and comprehensive protocol.

Methods: Patients referred for family screening after sudden cardiac death (SCD) of a family member were, retrospectively, enrolled into the study. Systematic evaluation of the children included clinical examination, family history, electrocardiogram (ECG), echocardiogram, 24-hour tape, and signal-averaged ECG. Older patients also underwent exercise testing, cardiac magnetic resonance imaging, and ajmaline provocation testing.

Results: A total of 90 children from 52 consecutive families were included in the study. An inherited cardiac disease was identified in seven first-degree children from seven (13.5%) families (five children were diagnosed with Brugada syndrome, one with long QT syndrome, and one with catecholaminergic polymorphic ventricular tachycardia). Two further children had late potentials on signal-averaged ECGs with no other abnormalities.

Conclusions: These data show a high prevalence of inherited heart disease in pediatric first-degree relatives of SADS victims. The results highlight the importance of a systematic, comprehensive approach and ongoing screening of pediatric family members.

Keywords: Brugada syndrome; arrhythmia; long QT syndrome; pediatric; screening; sudden death.

MeSH terms

  • Adolescent
  • Adult
  • Arrhythmias, Cardiac / complications
  • Child
  • Child, Preschool
  • Death, Sudden, Cardiac / etiology*
  • Female
  • Heart Diseases / complications*
  • Heart Diseases / diagnosis
  • Heart Diseases / genetics*
  • Humans
  • Infant
  • Male
  • Middle Aged
  • Retrospective Studies
  • Syndrome