Biosynthesis, characterization, and efficacy in retinal degenerative diseases of lens epithelium-derived growth factor fragment (LEDGF1-326), a novel therapeutic protein

J Biol Chem. 2013 Jun 14;288(24):17372-83. doi: 10.1074/jbc.M112.441618. Epub 2013 May 2.

Abstract

For vision-threatening retinitis pigmentosa and dry age-related macular degeneration, there are no United States Food and Drug Administration (FDA)-approved treatments. We identified, biosynthesized, purified, and characterized lens epithelium-derived growth factor fragment (LEDGF1-326) as a novel protein therapeutic. LEDGF1-326 was produced at about 20 mg/liter of culture when expressed in the Escherichia coli system, with about 95% purity and aggregate-free homogeneous population with a mean hydrodynamic diameter of 9 ± 1 nm. The free energy of unfolding of LEDGF1-326 was 3.3 ± 0.5 kcal mol(-1), and melting temperature was 44.8 ± 0.2 °C. LEDGF1-326 increased human retinal pigment epithelial cell viability from 48.3 ± 5.6 to 119.3 ± 21.1% in the presence of P23H mutant rhodopsin-mediated aggregation stress. LEDGF1-326 also increased retinal pigment epithelial cell FluoSphere uptake to 140 ± 10%. Eight weeks after single intravitreal injection in Royal College of Surgeons (RCS) rats, LEDGF1-326 increased the b-wave amplitude significantly from 9.4 ± 4.6 to 57.6 ± 8.8 μV for scotopic electroretinogram and from 10.9 ± 5.6 to 45.8 ± 15.2 μV for photopic electroretinogram. LEDGF1-326 significantly increased the retinal outer nuclear layer thickness from 6.34 ± 1.6 to 11.7 ± 0.7 μm. LEDGF1-326 is a potential new therapeutic agent for treating retinal degenerative diseases.

Keywords: Dry Age-related Macular Degeneration; Growth Factors; Lens Epithelium-derived Growth Factor; Protein Expression; Protein purification; Retinal Degeneration; Retinitis Pigmentosa; Therapeutic Protein; Transcription Factors.

Publication types

  • Research Support, N.I.H., Extramural

MeSH terms

  • Animals
  • Cell Line
  • Cell Shape / drug effects
  • Cell Survival / drug effects
  • Chromatography, High Pressure Liquid
  • Circular Dichroism
  • Cloning, Molecular
  • Electroretinography
  • Geographic Atrophy / drug therapy*
  • Geographic Atrophy / pathology
  • Humans
  • Injections, Intraocular
  • Intercellular Signaling Peptides and Proteins / administration & dosage*
  • Intercellular Signaling Peptides and Proteins / biosynthesis
  • Intercellular Signaling Peptides and Proteins / isolation & purification
  • Light
  • Molecular Weight
  • Particle Size
  • Peptide Fragments / administration & dosage*
  • Peptide Fragments / biosynthesis
  • Peptide Fragments / isolation & purification
  • Phagocytosis / drug effects
  • Protein Stability
  • Protein Structure, Secondary
  • Rats
  • Retinal Rod Photoreceptor Cells / drug effects
  • Retinal Rod Photoreceptor Cells / physiology
  • Retinitis Pigmentosa / drug therapy*
  • Retinitis Pigmentosa / pathology
  • Scattering, Radiation
  • Spectrometry, Mass, Matrix-Assisted Laser Desorption-Ionization
  • Stress, Physiological

Substances

  • Intercellular Signaling Peptides and Proteins
  • LEDGF1-326
  • Peptide Fragments