Characteristic scapular and rib changes on chest radiographs of children with ADA-deficiency SCIDS in the first year of life

Pediatr Radiol. 2013 Mar;43(5):589-92. doi: 10.1007/s00247-012-2564-2. Epub 2012 Nov 24.

Abstract

Background: We describe radiographic changes in the ribs and scapulae seen in the first 6 months of life in children with ADA (adenosine deaminase) deficiency severe combined immundeficiency syndrome (SCIDS). We suggest that these changes are reversible with appropriate enzyme replacement therapy.

Objective: The purpose of this study was to describe characteristic rib and scapular radiographic changes in infants with ADA-deficiency SCIDS.

Materials and methods: This was a retrospective review of chest radiographs of nine children with ADA-deficiency SCIDS performed in the first year of life by two experienced pediatric radiologists. A control cohort of unaffected children was used for comparison.

Results: All children with ADA-deficiency SCIDS manifested unusual scapular spurring and anterior rib cupping. None of the control children manifested these changes.

Conclusion: Characteristic and reversible scapular and rib changes in the correct clinical setting should suggest an early diagnosis of ADA deficiency, prompting appropriate diagnostic and therapeutic measures.

MeSH terms

  • Adenosine Deaminase / deficiency*
  • Agammaglobulinemia / diagnostic imaging*
  • Female
  • Humans
  • Infant
  • Infant, Newborn
  • Male
  • Radiography, Thoracic / methods*
  • Reproducibility of Results
  • Ribs / diagnostic imaging*
  • Scapula / diagnostic imaging*
  • Sensitivity and Specificity
  • Severe Combined Immunodeficiency / diagnostic imaging*

Substances

  • Adenosine Deaminase

Supplementary concepts

  • Severe combined immunodeficiency due to adenosine deaminase deficiency