Incidence of β-thalassemia carrier on 1495 couples in preconceptional period

J Matern Fetal Neonatal Med. 2013 Mar;26(5):445-8. doi: 10.3109/14767058.2012.735998. Epub 2012 Oct 30.

Abstract

Objective: This research, conducted on 1495 couples in preconceptional period, demonstrates how the study of globular resistance of erythrocytes (GRO) is not a first choice test and not useful as other more accurate tests to identify subjects with β-thalassemia trait. Instead, the complete blood count (CBC) and the evaluation of HbA, HbA2 and HbF by high pressure liquid chromatography (HPLC) are essential.

Methods: Each couple arrived in our laboratory to screen for β thalassemia. In case of patients with positive (240) or doubtful (112) results, we studied β-globin gene.

Results: Of the 2990 subjects examined, we found 280 subjects with β-thalassemia trait (9.36%). During biochemical tests, among 112 subjects with doubtful--normal GRO or altered GRO--results, 40 of them resulted positive for the molecular analysis, while 72 of them did not show mutations in β-globin genes. The 2710 samples with non-carriers of β-thalassemia trait presented as mean evaluation of HbA2 2.6%, while the 280 subjects with β-thalassemia trait presented as mean evaluation of HbA2 4.8%. Molecular study showed that the β thalassemia phenotype is caused by a small number of mutations, whose regional distribution is typical.

Conclusions: In the presence of thalassemic parameters in the CBC, the accurate and precise quantification of hemoglobin HbA2 is essential for the diagnosis of β-thalassemia trait. DNA mutation analysis provides the most effective way to detect primary gene mutations. The mutations identified in this work can be identified with a simple and inexpensive kit. This means, in economic terms, a significant savings for health spending.

MeSH terms

  • Blood Cell Count
  • Erythrocyte Indices
  • Fetal Hemoglobin / analysis
  • Genetic Carrier Screening / methods*
  • Hemoglobin A2 / analysis*
  • Humans
  • Italy / epidemiology
  • Male
  • Mutation
  • Osmotic Fragility
  • Preconception Care*
  • beta-Globins / genetics
  • beta-Thalassemia / blood
  • beta-Thalassemia / epidemiology
  • beta-Thalassemia / genetics*

Substances

  • beta-Globins
  • Hemoglobin A2
  • Fetal Hemoglobin