Annuloaortic ectasia in a 16 year-old boy with Loeys-Dietz syndrome

Heart Lung Circ. 2012 Apr;21(4):215-7. doi: 10.1016/j.hlc.2012.01.001. Epub 2012 Feb 9.

Abstract

Loeys-Dietz syndrome (LDS) is a rare genetic disorder with an autosomal dominant inheritance due to mutations in the transforming growth factor beta-receptor type 1 or type 2. The disease is characterised by the triad of hypertelorism, bifid uvula or cleft palate, arterial tortuosity and aortic aneurysms. These phenotypic characteristics distinguish LDS from other connective tissue disorders related to transforming growth factor beta-receptor. Patients with LDS have a high risk of aortic dissection or rupture at a younger age and smaller aortic diameters. So, clinical suspicion of LDS followed by genotyping is important to prevent aortic dissection, leading cause of death, by surgical treatment.

Publication types

  • Case Reports

MeSH terms

  • Abnormalities, Multiple / genetics*
  • Adolescent
  • Aorta / abnormalities*
  • Aorta / diagnostic imaging
  • Aorta / surgery
  • Aortography
  • Dilatation, Pathologic / congenital
  • Dilatation, Pathologic / diagnostic imaging
  • Dilatation, Pathologic / surgery
  • Humans
  • Loeys-Dietz Syndrome / genetics*
  • Loeys-Dietz Syndrome / surgery
  • Male
  • Mutation, Missense
  • Protein Serine-Threonine Kinases / genetics*
  • Receptor, Transforming Growth Factor-beta Type II
  • Receptors, Transforming Growth Factor beta / genetics*
  • Ultrasonography

Substances

  • Receptors, Transforming Growth Factor beta
  • Protein Serine-Threonine Kinases
  • Receptor, Transforming Growth Factor-beta Type II