[Mucopolysaccharidosis VII: report of a case and review of the literature]

Zhonghua Er Ke Za Zhi. 2011 Jun;49(6):455-8.
[Article in Chinese]

Abstract

Objective: To investigate the clinical characteristics and diagnosis of mucopolysaccharidosis VII.

Method: The clinical and biochemical features of an infant with mucopolysaccharidosis VII confirmed by enzyme assay were analyzed.

Result: The 2 month-old male infant showed hydrops fetalis, mental retardation, coarse face, corneal clouding, hepatosplenomegaly, hernias, Alder-Reilly granules in the leucocytes and decreased platelet (32 × 10(9)/L). The biochemical markers showed urinary glycosaminoglycans (GAG) (532.8 mg/L, controls < 70.0 mg/L). The ratio of GAG/creatinine was 161.3 (controls: 26.2 ± 11.7). Serum chitotriosidase activity was 315.8 nmol/(ml·h) [control < 53 nmol/(ml·h)]. Beta-glucuronidase activity was deficient in isolated leukocytes.

Conclusion: Severe form of mucopolysaccharidosis VII exhibited characteristics of hydrops fetalis, hepatosplenomegaly, coarse face, thrombocytopenia and Alder-Reilly granules in the leucocytes. The measurements of GAG in urinary and beta glucuronidase in leucocytes are critical to diagnosis and deferential diagnosis.

Publication types

  • Case Reports
  • English Abstract
  • Research Support, Non-U.S. Gov't
  • Review

MeSH terms

  • Glucuronidase / metabolism
  • Glycosaminoglycans / urine
  • Humans
  • Infant
  • Leukocytes / enzymology
  • Male
  • Mucopolysaccharidosis VII*

Substances

  • Glycosaminoglycans
  • Glucuronidase