Aberrant frontal lobe maturation in adolescents with fragile X syndrome is related to delayed cognitive maturation

Biol Psychiatry. 2011 Nov 1;70(9):852-8. doi: 10.1016/j.biopsych.2011.05.038. Epub 2011 Jul 29.

Abstract

Background: Fragile X syndrome (FXS) is the most common known heritable cause of intellectual disability. Prior studies in FXS have observed a plateau in cognitive and adaptive behavioral development in early adolescence, suggesting that brain development in FXS may diverge from typical development during this period.

Methods: In this study, we examined adolescent brain development using structural magnetic resonance imaging data acquired from 59 individuals with FXS and 83 typically developing control subjects aged 9 to 22, a subset of whom were followed up longitudinally (1-5 years; typically developing: 17, FXS: 19). Regional volumes were modeled to obtain estimates of age-related change.

Results: We found that while structures such as the caudate showed consistent volume differences from control subjects across adolescence, prefrontal cortex (PFC) gyri showed significantly aberrant maturation. Furthermore, we found that PFC-related measures of cognitive functioning followed a similarly aberrant developmental trajectory in FXS.

Conclusions: Our findings suggest that aberrant maturation of the PFC during adolescence may contribute to persistent or increasing intellectual deficits in FXS.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Aging / physiology
  • Child
  • Cognition / physiology*
  • Female
  • Follow-Up Studies
  • Fragile X Syndrome / pathology*
  • Fragile X Syndrome / psychology*
  • Frontal Lobe / growth & development*
  • Frontal Lobe / pathology*
  • Humans
  • Image Processing, Computer-Assisted
  • Magnetic Resonance Imaging
  • Male
  • Neuropsychological Tests
  • Prefrontal Cortex / growth & development
  • Prefrontal Cortex / pathology
  • Young Adult