Mitochondrial transfer RNA(Phe) mutation associated with a progressive neurodegenerative disorder characterized by psychiatric disturbance, dementia, and akinesia-rigidity

Arch Neurol. 2010 Nov;67(11):1399-402. doi: 10.1001/archneurol.2010.283.

Abstract

Background: Mitochondrial diseases are characterized by wide phenotypic and genetic variability, but presentations in adults with akinetic rigidity and hyperkinetic movement disorders are rare.

Objectives: To describe clinically a subject with progressive neurodegeneration characterized by psychosis, dementia, and akinesia-rigidity, and to associate this phenotype with a novel mitochondrial transfer RNA(Phe) (tRNA(Phe)) (MTTF) mutation.

Design, setting, and patient: Case description and detailed laboratory investigations of a 57-year-old woman at a university teaching hospital and a specialist mitochondrial diagnostic laboratory.

Results: Histopathological findings indicated that an underlying mitochondrial abnormality was responsible for the subject's progressive neurological disorder, with mitochondrial genome sequencing revealing a novel m.586G>A MTTF mutation.

Conclusions: The clinical phenotypes associated with mitochondrial disorders may include akinesia-rigidity and psychosis. Our findings further broaden the spectrum of neurological disease associated with mitochondrial tRNA(Phe) mutations.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Atrophy / genetics
  • Atrophy / pathology
  • Atrophy / physiopathology
  • Brain / pathology
  • Brain / physiopathology
  • Dementia / genetics*
  • Dementia / pathology
  • Dementia / physiopathology
  • Disease Progression
  • Female
  • Humans
  • Magnetic Resonance Imaging
  • Middle Aged
  • Mitochondrial Diseases / genetics*
  • Mitochondrial Diseases / pathology
  • Mitochondrial Diseases / physiopathology
  • Muscle Rigidity / genetics*
  • Muscle Rigidity / pathology
  • Muscle Rigidity / physiopathology
  • Mutation*
  • Neurodegenerative Diseases / genetics*
  • Neurodegenerative Diseases / pathology
  • Neurodegenerative Diseases / physiopathology
  • Neuropsychological Tests
  • Phenylalanine / genetics
  • RNA, Transfer / genetics*

Substances

  • Phenylalanine
  • RNA, Transfer