A novel frame-shift deletion causing analbuminaemia in an Italian paediatric patient

Eur J Clin Invest. 2010 Mar;40(3):281-4. doi: 10.1111/j.1365-2362.2010.02256.x.

Abstract

Background: Analbuminaemia (OMIM #103600) is a rare autosomal recessive disorder manifested by the absence or severe reduction of circulating serum albumin in homozygous or compound heterozygous subjects. The trait is caused by a variety of mutations within the albumin gene.

Design: We report here the clinical and molecular characterization of a new case of congenital analbuminaemia in a 4-year-old Italian girl diagnosed on the basis of the low level of circulating albumin (= 10.0 g L(-1)). The albumin gene was screened by single-strand conformation polymorphism and heteroduplex analysis and the mutated region submitted to DNA sequencing.

Results: The proband was found to be homozygous, and both parents heterozygous, for a novel deletion in exon 8 (c.920delT). The subsequent frame-shift should have given rise to a putative polypeptide chain of 304 amino acid residues, which we could not identify in the proband's serum.

Conclusions: A novel analbuminaemia causing mutation was identified and characterized at the clinical level in a child. The molecular diagnosis of the trait is based on the rapid localization of the mutation within the albumin gene by single-strand conformation polymorphism and heteroduplex analysis, followed by DNA sequencing of the mutated region.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Child
  • DNA Mutational Analysis*
  • Exons / genetics
  • Female
  • Frameshift Mutation
  • Humans
  • Italy
  • Polymorphism, Single-Stranded Conformational
  • Serum Albumin / deficiency*
  • Serum Albumin / genetics*

Substances

  • Serum Albumin