TREX1 mutations are not associated with sporadic inclusion body myositis

Eur J Neurol. 2010 Aug;17(8):1108-9. doi: 10.1111/j.1468-1331.2010.02964.x. Epub 2010 Feb 23.

Abstract

Background: Sporadic inclusion body myositis (sIBM) is the most frequent acquired myopathy above the age of fifty. The exact mechanism causing this disease is not known, but immune-mediated features are prominent and are probably to play a role in its pathogenesis. TREX1 gene mutations are associated with a large range of autoimmune diseases, such as systemic lupus erythematosus. We investigated whether mutations in the TREX1 gene were associated with sIBM.

Methods: Fifty-four patients with sIBM were tested for TREX1 mutations by direct sequencing.

Results: All 54 patients tested negative for pathogenic mutations in the TREX1 gene. One presumed non-pathogenic polymorphism was found in 42 out of 54 patients.

Conclusion: TREX1 mutations do not play a role in the pathogenesis of sIBM.

MeSH terms

  • Aged
  • Aged, 80 and over
  • Exodeoxyribonucleases / genetics*
  • Female
  • Genetic Predisposition to Disease
  • Humans
  • Male
  • Middle Aged
  • Mutation
  • Myositis, Inclusion Body / genetics*
  • Phosphoproteins / genetics*

Substances

  • Phosphoproteins
  • Exodeoxyribonucleases
  • three prime repair exonuclease 1