A comprehensive genetic study of the proteasomal subunit S6 ATPase in German Parkinson's disease patients

J Neural Transm (Vienna). 2008 Aug;115(8):1141-8. doi: 10.1007/s00702-008-0054-3. Epub 2008 Apr 30.

Abstract

Dysfunction of proteasomal protein degradation is involved in neurodegeneration in Parkinson's disease (PD). Recently we identified the regulatory proteasomal subunit S6 ATPase as a novel interactor of synphilin-1, which is a substrate of the ubiquitin-ligase Parkin (PARK2) and an interacting protein of alpha-synuclein (PARK1). To further investigate a potential role in the pathogenesis of PD, we performed a detailed mutation analysis of the S6 ATPase gene in a large sample of 486 German sporadic and familial PD patients. Direct sequencing revealed two novel intronic variants. An insertion/deletion variant in intron 5 of the S6 ATPase gene was more frequent in patients compared to controls. Moreover, this variant was significantly more frequent in early-onset compared to late-onset PD patients. The identification of a genetic link between a regulatory proteasomal subunit and PD further underscores the relevance of disturbed protein degradation in PD.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • ATPases Associated with Diverse Cellular Activities
  • Adenosine Triphosphatases / genetics*
  • Aged
  • Alleles
  • Carrier Proteins / genetics
  • Chromatography, High Pressure Liquid
  • DNA Mutational Analysis
  • DNA, Complementary / biosynthesis
  • DNA, Complementary / genetics
  • Female
  • Genotype
  • Germany / epidemiology
  • Humans
  • Introns / genetics
  • Male
  • Middle Aged
  • Nerve Tissue Proteins / genetics
  • Parkinson Disease / epidemiology*
  • Parkinson Disease / genetics*
  • Polymorphism, Restriction Fragment Length
  • Proteasome Endopeptidase Complex / genetics*
  • Protein Denaturation
  • RNA, Messenger / biosynthesis
  • RNA, Messenger / genetics
  • Reverse Transcriptase Polymerase Chain Reaction

Substances

  • Carrier Proteins
  • DNA, Complementary
  • Nerve Tissue Proteins
  • RNA, Messenger
  • SNCAIP protein, human
  • PSMC4 protein, human
  • Proteasome Endopeptidase Complex
  • Adenosine Triphosphatases
  • ATPases Associated with Diverse Cellular Activities