[Benign solitary fibrous pleural tumour and hypoglycaemia]

Srp Arh Celok Lek. 2007 May-Jun;135(5-6):326-9. doi: 10.2298/sarh0706326m.
[Article in Serbian]

Abstract

Introduction: Solitary fibrous tumours of the pleura are uncommon and discovered fortuitously or in patients with non-specific respiratory symptoms. When associated with hypoglycaemia, they are commonly referred to as Doege-Potter syndrome.

Case outline: A 68-year old woman presented with a large pleural mass. She had a long history of headache and decreased consciousness with one-year worsening dyspnoea and right-sided chest pain. The chest X-ray revealed an enormous opacity occupying almost the entire right hemithorax. Endocrine tests showed an extremely reduced glucose level and blood concentration of insulin, C-peptide, glucagon, growth hormone and catecholamines within normal range. After fine-needle aspiration, by histological and immunohistochemical analysis, a benign solitary fibrous pleural tumour was diagnosed. Although surgical resection of such a huge tumour with hypoglycaemia is usually curative, our patient declined surgery and opted for conservative treatment with intravenous glucose.

Conclusion: Clinicians should be aware of this rare, but important cause of hypoglycaemia and exclude a fibrous pleural tumour in the assessment of their patients.

Publication types

  • Case Reports
  • English Abstract

MeSH terms

  • Aged
  • Female
  • Humans
  • Hypoglycemia / etiology*
  • Neoplasms, Fibrous Tissue / complications*
  • Paraneoplastic Syndromes*
  • Pleural Neoplasms / complications*