Ophthalmic manifestations of Sanjad-Sakati syndrome

Ophthalmic Genet. 2006 Sep;27(3):83-7. doi: 10.1080/13816810600862568.

Abstract

Background: Sanjad-Sakati syndrome (SSS) is a rare disorder characterized by hypoparathyroidism, growth and developmental delay, and dysmorphism. The purpose of this report is to describe the ophthalmic manifestations of Sanjad-Sakati syndrome (SSS; hypoparathyroidism-mental retardation-dysmorphism syndrome, HRD) (OMIM 241410).

Patients: We included a total of 17 patients who were seen at two hospitals in Riyadh.

Methods: Each patient underwent a complete ophthalmologic evaluation including visual acuity assessment, orthoptic workup, slit-lamp biomicroscopy, intraocular pressure measurement, cycloplegic retinoscopy, funduscopy, corneal diameter, and axial length measurement.

Results: All 17 (100%) of the patients had normal visual acuity. All patients had microphthalmia with normal intraocular pressure. Eight (47%) of the patients had esotropia and four (23%) had exotropia. Ophthalmoscopy revealed tortuous retinal blood vessels in all patients. Hyperopic astigmatism was present in 16 (94%) patients.

Conclusion: Patients with SSS display a variety of ocular findings including errors of refraction, strabismus, and retinal vascular tortuousity.

MeSH terms

  • Adolescent
  • Astigmatism / etiology
  • Astigmatism / genetics
  • Child
  • Child, Preschool
  • Craniofacial Abnormalities / complications*
  • Craniofacial Abnormalities / genetics
  • Developmental Disabilities / complications
  • Developmental Disabilities / genetics
  • Eye Diseases / etiology*
  • Eye Diseases / genetics
  • Female
  • Humans
  • Hypoparathyroidism / complications*
  • Hypoparathyroidism / genetics
  • Infant
  • Intellectual Disability / complications*
  • Intellectual Disability / genetics
  • Intraocular Pressure
  • Male
  • Microphthalmos / etiology
  • Microphthalmos / genetics
  • Retinal Diseases / etiology
  • Retinal Diseases / genetics
  • Retinal Vessels / abnormalities
  • Retinoscopy
  • Strabismus / etiology
  • Strabismus / genetics
  • Syndrome

Associated data

  • OMIM/146200
  • OMIM/188400
  • OMIM/241410
  • OMIM/244460
  • OMIM/307700