Phase II trial of pirfenidone in adults with neurofibromatosis type 1

Neurology. 2006 Nov 28;67(10):1860-2. doi: 10.1212/01.wnl.0000243231.12248.67. Epub 2006 Oct 11.

Abstract

We performed an open-label phase II trial of oral pirfenidone in 24 patients with neurofibromatosis type 1 (NF1). Tumors were monitored by three-dimensional MRI. At the end of treatment, four patients had a decrease in tumor volume by 15% or more, three had tumor progression, and 17 remained stable. Pirfenidone warrants further investigation in NF1, which has until now lacked an effective control therapy.

Publication types

  • Clinical Trial, Phase II
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Antineoplastic Agents / administration & dosage*
  • Antineoplastic Agents / adverse effects
  • Dose-Response Relationship, Drug
  • Drug Administration Schedule
  • Female
  • Humans
  • Magnetic Resonance Imaging
  • Male
  • Middle Aged
  • Neuralgia / drug therapy
  • Neuralgia / etiology
  • Neuralgia / physiopathology
  • Neurofibroma / drug therapy
  • Neurofibroma / pathology
  • Neurofibroma / physiopathology
  • Neurofibromatosis 1 / drug therapy*
  • Neurofibromatosis 1 / pathology
  • Neurofibromatosis 1 / physiopathology
  • Peripheral Nerves / drug effects
  • Peripheral Nerves / pathology
  • Peripheral Nerves / physiopathology
  • Peripheral Nervous System Neoplasms / drug therapy
  • Peripheral Nervous System Neoplasms / pathology
  • Peripheral Nervous System Neoplasms / physiopathology
  • Pyridones / administration & dosage*
  • Pyridones / adverse effects
  • Treatment Outcome

Substances

  • Antineoplastic Agents
  • Pyridones
  • pirfenidone