Stickler syndrome type I and Stapes ankylosis

Int J Pediatr Otorhinolaryngol. 2004 Dec;68(12):1573-80. doi: 10.1016/j.ijporl.2004.07.015.

Abstract

Objective: To report a successful stapedectomy for stapedial fixation in a patient with Stickler syndrome type I (COL2A1).

Setting: University Hospital Department for Otology, Pathology, Ophthalmology and Clinical Genetics.

Study design: A clinical and genetic evaluation of a mother and daughter focusing mainly on the otological, ophthalmological, histological and genetical aspects.

Intervention: A stapedectomy was performed successfully.

Results: Hearing impairment improved after stapedectomy. Postoperatively a shift in high-frequency threshold wa seen related to the stapedectomy. A new mutation in COL2A1 gene was dectected.

Conclusion: Stapedial fixation can be the cause of hearing impairment in Stickler syndrome type I (COL2A1). The hearing impairment can be improved by stapes surgery.

Publication types

  • Case Reports

MeSH terms

  • Abnormalities, Multiple / genetics
  • Abnormalities, Multiple / pathology*
  • Abnormalities, Multiple / surgery
  • Adolescent
  • Adult
  • Collagen Type II / genetics
  • Connective Tissue Diseases / pathology
  • Family Health
  • Female
  • Hearing Loss, Sensorineural / pathology*
  • Humans
  • Mutation
  • Myopia / pathology
  • Stapes / abnormalities*
  • Stapes Surgery
  • Syndrome

Substances

  • COL2A1 protein, human
  • Collagen Type II