Modulation of notch processing by gamma-secretase inhibitors causes intestinal goblet cell metaplasia and induction of genes known to specify gut secretory lineage differentiation

Toxicol Sci. 2004 Nov;82(1):341-58. doi: 10.1093/toxsci/kfh254. Epub 2004 Aug 19.

Abstract

It is anticipated that gamma-secretase inhibitors (gamma-Sec-I) that modulate Notch processing will alter differentiation in tissues whose architecture is governed by Notch signaling. To explore this hypothesis, Han Wistar rats were dosed for up to 5 days with 10-100 micromol/kg b.i.d. gamma-Sec-I from three chemical series that inhibit Notch processing in vitro at various potencies (Notch IC(50)). These included an arylsulfonamide (AS) (142 nM), a dibenzazepine (DBZ) (1.7 nM), and a benzodiazepine (BZ) (2.2 nM). The DBZ and BZ caused dose-dependent intestinal goblet cell metaplasia. In contrast, the AS produced no detectable in vivo toxicity, despite higher exposure to free drug. In a time course using BZ, small intestinal crypt cell and large intestinal glandular cell epithelial apoptosis was observed on days 1-5, followed by goblet cell metaplasia on days 2-5 and crypt epithelial and glandular epithelial regenerative hyperplasia on days 4-5. Gene expression profiling of duodenal samples from BZ-dosed animals revealed significant time-dependent deregulation of mRNAs for various panendocrine, hormonal, and transcription factor genes. Somatostatin, secretin, mucin, CCK, and gastrin mRNAs were elevated twofold or more by day 2, and a number of candidate "early-predictive" genes were altered on days 1-2, remaining changed for 4-5 days; these included Delta1, NeuroD, Hes1-regulated adipsin, and the Hes-regulated transcriptional activator of gut secretory lineage differentiation, the rat homolog of Drosophila atonal, Rath1. Western blotting of fecal protein from BZ-and DBZ-dosed animals exhibited increased levels of both anti-Rath1 reactive protein and anti-adipsin reactive proteins, confirming their potential value as noninvasive biomarkers of intestinal goblet metaplasia.

MeSH terms

  • Amyloid Precursor Protein Secretases
  • Animals
  • Apoptosis / drug effects
  • Aspartic Acid Endopeptidases
  • Benzodiazepines / pharmacology
  • Biomarkers / analysis
  • Cell Differentiation / drug effects
  • Cell Line, Tumor
  • Dibenzazepines / pharmacology
  • Dose-Response Relationship, Drug
  • Endopeptidases* / metabolism
  • Enzyme Inhibitors / pharmacology*
  • Gene Expression Regulation / drug effects*
  • Goblet Cells / metabolism*
  • Goblet Cells / pathology
  • Humans
  • Male
  • Metaplasia
  • RNA, Messenger / analysis
  • Rats
  • Rats, Wistar
  • Receptor, Notch1
  • Receptors, Cell Surface / genetics
  • Receptors, Cell Surface / metabolism*
  • Signal Transduction
  • Sulfonamides / pharmacology
  • Transcription Factors / genetics
  • Transcription Factors / metabolism*

Substances

  • Biomarkers
  • Dibenzazepines
  • Enzyme Inhibitors
  • NOTCH1 protein, human
  • Notch1 protein, rat
  • RNA, Messenger
  • Receptor, Notch1
  • Receptors, Cell Surface
  • Sulfonamides
  • Transcription Factors
  • Benzodiazepines
  • Amyloid Precursor Protein Secretases
  • Endopeptidases
  • Aspartic Acid Endopeptidases
  • BACE1 protein, human