Primary central nervous system sarcomas in children: clinical, radiological, and pathological features

Childs Nerv Syst. 2003 Dec;19(12):808-17. doi: 10.1007/s00381-003-0839-5. Epub 2003 Oct 22.

Abstract

Patients and methods: The clinical, radiological, surgical, and pathological findings of 16 children with a primary central nervous system (CNS) sarcoma are reported. There were 8 (50%) girls and 8 (50%) boys ranging in age from 4 months to 14 years (mean age 4.8 years). Four patients (23%) were in their 1st year of life. Fourteen children (87%) had an intracranial sarcoma, and 2 (13%) had intraspinal tumors. Nine intracranial tumors (60%) were supratentorial. The parietal and temporal regions were the most frequently involved sites.

Results: Characteristic imaging findings included tumor cysts in 7 patients and marked tumoral enhancement in 9 (69%) with intratumoral calcification and hemorrhage. All patients underwent at least one operation to surgically remove the tumor with the aim of maximal resection and 3 patients underwent a second resection due to a recurrent tumor. Resection was total in 9 (53%) patients and subtotal in another 7 (41%). Dural attachment by tumor was confirmed in 7 (44%) patients and parenchymal invasion was present in 9 (56%). In one-third of the patients there was a well-defined plane of dissection around the tumor. Postoperative radiation was used in 10 patients. Postoperative chemotherapy was used in all but 2 patients. Immunohistochemical studies were available in 13 patients with the most consistent finding being strong vimentin positivity. Five out of the 6 patients in whom the proliferation markers were obtained demonstrated a high proliferation index (Ki-67 labeling index, 20-50%). The mean length of survival in the group was 4.6 years (range 1 month to 16 years). Children who presented in the 1st year of life had shorter survival than those who presented at an older age. Six patients (40%) had cerebrospinal fluid (CSF) dissemination of the tumor. CSF dissemination was associated with a shorter mean survival of 1.9 years.

Conclusions: Our review of this series of patients indicates the requirement for adjuvant therapy and for continued efforts to classify tumor subtypes aimed at optimizing future treatments for patients with a primary CNS sarcoma.

Publication types

  • Comparative Study
  • Review

MeSH terms

  • Central Nervous System / diagnostic imaging
  • Central Nervous System / pathology
  • Central Nervous System / physiopathology
  • Central Nervous System Neoplasms* / diagnostic imaging
  • Central Nervous System Neoplasms* / epidemiology
  • Central Nervous System Neoplasms* / pathology
  • Central Nervous System Neoplasms* / therapy
  • Child
  • Child, Preschool
  • Combined Modality Therapy
  • Female
  • Follow-Up Studies
  • Humans
  • Infant
  • Magnetic Resonance Imaging
  • Male
  • Sarcoma* / diagnostic imaging
  • Sarcoma* / epidemiology
  • Sarcoma* / pathology
  • Sarcoma* / therapy
  • Survival Rate
  • Tomography, X-Ray Computed / methods
  • Treatment Outcome