[Amyloid neuropathies. Histopathological study of peripheral nerve biopsy in 18 cases]

Ann Pathol. 2003 Apr;23(2):114-20.
[Article in French]

Abstract

Objectives: A retrospective study of nerve and muscle biopsies since 1983, with probable amyloidosis, has been performed.

Materials and methods: Eighteen nerve and muscle biopsies, out of 29, were selected.

Results: Endoneurial amyloid deposits were visible on routine sections in 11 cases, revealed by ultrastructural study in 4 cases and by Congo red and/or thioflavine stains in 3 others. Amyloid deposits were marked by anti-transthyretin (TTR) serum in 13 patients, within endoneurium in 11 cases, and only around muscle fibers in 2 others. A mutation in the TTR gene, usually Val30Met, was evidenced in 8 cases and could not be assayed in the 5 others. An immunoglobulin light chain was revealed in amyloid deposits by direct immunofluorescence in the 5 other patients, of whom 4 had multiple myeloma and the fifth a lambda light chain Bence-Jones proteinuria.

Conclusion: Nerve biopsy revealed amyloidosis in 10 patients: 5 of them had a mutation in TTR gene, without any family history.

Publication types

  • English Abstract

MeSH terms

  • Adult
  • Aged
  • Amyloid / analysis
  • Amyloidosis / genetics
  • Amyloidosis / pathology*
  • Bence Jones Protein / urine
  • Biopsy
  • Female
  • Humans
  • Immunoglobulin Light Chains / analysis
  • Immunoglobulin lambda-Chains / analysis
  • Male
  • Middle Aged
  • Multiple Myeloma / pathology
  • Mutation
  • Nervous System Diseases / genetics
  • Nervous System Diseases / pathology*
  • Prealbumin / genetics
  • Retrospective Studies

Substances

  • Amyloid
  • Immunoglobulin Light Chains
  • Immunoglobulin lambda-Chains
  • Prealbumin
  • Bence Jones Protein