Correlation between automated writing movements and striatal dopaminergic innervation in patients with Wilson's disease

J Neurol. 2002 Aug;249(8):1082-7. doi: 10.1007/s00415-002-0795-0.

Abstract

Handwriting defects are an early sign of motor impairment in patients with Wilson's disease. The basal ganglia being the primary site of copper accumulation in the brain suggests a correlation with lesions in the nigrostiatal dopaminergic system. We have analysed and correlated striatal dopaminergic innervation using [(123)I]beta-CIT-SPECT and automated handwriting movements in 37 patients with Wilson's disease. There was a significant correlation of putaminal dopaminergic innervation with fine motor ability (p < 0,05 for NIV [number of inversion in velocity], NIA [number of inversion in acceleration], frequency). These data suggest that loss of dorsolateral striatal dopaminergic innervation has a pathophysiological function for decreased automated motor control in Wilson's disease. Furthermore analysis of automated handwriting movements could be useful for therapy monitoring and evaluation of striatal dopaminergic innervation.

MeSH terms

  • Adult
  • Age Factors
  • Aged
  • Corpus Striatum / metabolism*
  • Dopamine Plasma Membrane Transport Proteins
  • Female
  • Handwriting*
  • Hepatolenticular Degeneration / physiopathology*
  • Humans
  • Male
  • Membrane Glycoproteins*
  • Membrane Transport Proteins / metabolism*
  • Middle Aged
  • Motor Skills / physiology
  • Nerve Tissue Proteins*
  • Sex Factors
  • Tomography, Emission-Computed, Single-Photon*

Substances

  • Dopamine Plasma Membrane Transport Proteins
  • Membrane Glycoproteins
  • Membrane Transport Proteins
  • Nerve Tissue Proteins