[A study of gene products encoded by Wilson disease gene]

Zhonghua Gan Zang Bing Za Zhi. 2001 Apr;9(2):86-8.
[Article in Chinese]

Abstract

Objective: To investigate the pathogenesis of Wilson disease (WD) by detecting its gene products encoded by WD gene (ATP7B).

Methods: Patients diagnosed as WD were analyzed by SDS-PAGE in conjunction with Western blot. Two antibodies were used, which are specially against the sixth copper binding domain (Anti-CuBD) and ATP binding domain (Anti-ABD) of WD protein.

Results: The WD proteins were not expressed in two patients when using anti-CuBD, and poorly expressed when using anti-ABD.

Conclusions: WD is highly heterogeneous in clinical manifestations and inheritance pattern. Two WD patients might simultaneously have exon 5 mutations and exon 8 mutations. The study of WD gene products would probe into the pathogenesis of WD.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adenosine Triphosphatases / analysis*
  • Adolescent
  • Adult
  • Carrier Proteins / analysis*
  • Cation Transport Proteins*
  • Copper-Transporting ATPases
  • Female
  • Hepatolenticular Degeneration / etiology
  • Hepatolenticular Degeneration / genetics*
  • Humans
  • Male
  • Mutation

Substances

  • Carrier Proteins
  • Cation Transport Proteins
  • Adenosine Triphosphatases
  • ATP7B protein, human
  • Copper-Transporting ATPases